Brain cell type-specific enhancer-promoter interactome maps and disease - risk association

Science. 2019 Nov 29;366(6469):1134-1139. doi: 10.1126/science.aay0793. Epub 2019 Nov 14.

Abstract

Noncoding genetic variation is a major driver of phenotypic diversity, but functional interpretation is challenging. To better understand common genetic variation associated with brain diseases, we defined noncoding regulatory regions for major cell types of the human brain. Whereas psychiatric disorders were primarily associated with variants in transcriptional enhancers and promoters in neurons, sporadic Alzheimer's disease (AD) variants were largely confined to microglia enhancers. Interactome maps connecting disease-risk variants in cell-type-specific enhancers to promoters revealed an extended microglia gene network in AD. Deletion of a microglia-specific enhancer harboring AD-risk variants ablated BIN1 expression in microglia, but not in neurons or astrocytes. These findings revise and expand the list of genes likely to be influenced by noncoding variants in AD and suggest the probable cell types in which they function.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adaptor Proteins, Signal Transducing / genetics*
  • Alzheimer Disease / genetics*
  • Brain / metabolism*
  • Cells, Cultured
  • Chromatin / metabolism
  • Enhancer Elements, Genetic / genetics*
  • Gene Regulatory Networks
  • Genetic Variation*
  • Genome-Wide Association Study
  • Humans
  • Microglia / metabolism*
  • Nuclear Proteins / genetics*
  • Promoter Regions, Genetic / genetics*
  • Sequence Deletion
  • Tumor Suppressor Proteins / genetics*

Substances

  • Adaptor Proteins, Signal Transducing
  • BIN1 protein, human
  • Chromatin
  • Nuclear Proteins
  • Tumor Suppressor Proteins